scholarly journals Spontaneously Regressing Neonatal Oral Aphthous Ulceration of the Palate

2021 ◽  
Vol 2021 ◽  
pp. 1-3
Author(s):  
Sandara Wayangi Madurapperuma ◽  
Andra Hennadige Heshan Malinga Jayaweera ◽  
Ruwan Duminda Jayasinghe
Keyword(s):  
Clinical Presentation ◽  
Rare Presentation ◽  
Diagnostic Dilemma ◽  
Nasogastric Feeding ◽  
Case Presentation ◽  
Uncommon Presentation ◽  
Appropriate Treatment ◽  
Aphthous Ulceration ◽  
Mild Fever ◽  
Ongoing Infection

Background. Neonatal oral aphthous ulceration of the palate also known as Bednar’s aphthae is not an uncommon presentation. They clinically present as spontaneously regressing, shallow, and symmetrical ulcers on the posterior palate of newborns from 2 days up to 6 weeks of age. Case Presentation. We, herein, report a case of a one-month-old baby girl who presented with an ulcer in the posterior palate and intermittent mild fever. The patient was admitted and monitored in the ward. Haematologic investigations disclosed features of ongoing infection. Nasogastric feeding was commenced to avoid any irritation of the ulcer, and glycerine was applied on the ulcer. Antibiotic therapy was continued because of the intermittent mild fever. The lesion healed spontaneously within one week, and fever subsided afterwards. Currently, the patient is faring healthily without any complications. Conclusion. Although Bednar’s aphthae is not a rare presentation, clinicians are often met with a diagnostic dilemma due to the alarming clinical presentation of this condition. Therefore, it leads to overinvestigation and overtreatment. With this case report, we would like to highlight the importance of being aware of this condition to provide the patients with the appropriate treatment.

scholarly journals Pyoderma Gangrenosum-like ulceration as a presenting feature of pediatric Granulomatosis with Polyangiitis

2020 ◽  
Author(s):  
Rotem Semo Oz ◽  
Oluwakemi Onajin ◽  
Liora Harel ◽  
Rotem Tal ◽  
Tomas Dallos ◽  
...  
Keyword(s):  
Pyoderma Gangrenosum ◽  
Granulomatosis With Polyangiitis ◽  
Skin Lesions ◽  
Response To Treatment ◽  
Newly Diagnosed ◽  
Rare Presentation ◽  
Case Presentation ◽  
Appropriate Treatment ◽  
The Mean ◽  
Systemic Symptoms

Abstract Background: Granulomatosis with polyangiitis (GPA) is an anti-neutrophilic cytoplasmic antibody-associated vasculitis affecting small to medium-sized vessels and involves most commonly the kidneys and the respiratory tract. Skin involvement can be seen in up to 50% of children with GPA and is the initial presenting symptom in 7.7%. Pyoderma gangrenosum (PG)-like ulcers are rarely described as a skin manifestation in GPA and very few cases have been reported previously in children. Case presentation: We describe 3 new pediatric cases of GPA with PG-like ulcerations. The mean age at first symptom was 15 years. Two patients had PG-like ulceration as their initial presentation; additional symptoms eventually led to the diagnosis of GPA 2-24 months later. In 1 case, proteinase 3 (PR3) was negative when first tested, but converted to positive when systemic symptoms emerged, in the other 2 cases PR3 was positive at presentation. All 3 patients had prominent facial lesions. None of the patients responded to treatment with antibiotics or medications commonly used to manage PG, including corticosteroids and cyclosporine. All patients had excellent responses to rituximab. An electronic database literature review was performed and 4 previously reported cases were identified. We assessed the clinical characteristics, serology, and response to treatment of 4 previously reported and newly diagnosed cases. Conclusion: PG-like ulceration is a rare presentation of pediatric GPA which may precede classic systemic GPA symptoms. The predominance of facial ulcer, granulomatous and neutrophilic inflammation on skin biopsy and lack of response to PG treatments are characteristic of GPA-associated PG-like ulcers. Our review suggests that treatment with rituximab may be needed to improve the skin lesions. Recognizing that PG-like ulcerations can occur in pediatric GPA may result in timely diagnosis, appropriate treatment and improved prognosis.

scholarly journals Upper Abdominal Primary Retroperitoneal Cyst with Unusual Urothelial Histogenesis - An Uncommon Presentation Masquerading as a Hepatic Cyst

2020 ◽  
pp. 1-3
Author(s):  
Arun Gopinath ◽  
Ahmad Alkhasawneh ◽  
Arun Gopinath ◽  
Brett Baskovich ◽  
Civan Altunkaynak ◽  
...  
Keyword(s):  
Clinical Presentation ◽  
Laparoscopic Resection ◽  
Hepatic Cyst ◽  
Rare Occurrence ◽  
Case Presentation ◽  
Uncommon Presentation ◽  
Retroperitoneal Cyst ◽  
Rare Lesion ◽  
Upper Abdominal ◽  
Primary Retroperitoneal

Background: Benign retroperitoneal cysts are uncommon. There is a paucity of literature on primary upper abdominal retroperitoneal cysts of urothelial histogenesis. We report an uncommon presentation of urothelial cyst clinically mimicking a hepatic cyst. Case presentation: A 21-year old female patient was admitted with intermittent abdominal pain of 9 months duration diagnosed on radiology as a right hepatic cyst. Laparoscopic resection and pathologic examination revealed a primary retroperitoneal cyst with a urothelial histogenesis. This is an unusual clinical presentation of a rare lesion mimicking a hepatic cyst. Conclusion: This case highlights the unusual anatomic location and the rare occurrence of an upper abdominal retroperitoneal urothelial cyst.

scholarly journals Pyoderma gangrenosum-like ulceration as a presenting feature of pediatric granulomatosis with polyangiitis

2021 ◽  
Vol 19 (1) ◽  
Author(s):  
Rotem Semo Oz ◽  
Oluwakemi Onajin ◽  
Liora Harel ◽  
Rotem Tal ◽  
Tomas Dallos ◽  
...  
Keyword(s):  
Pyoderma Gangrenosum ◽  
Granulomatosis With Polyangiitis ◽  
Skin Lesions ◽  
Response To Treatment ◽  
Proteinase 3 ◽  
Newly Diagnosed ◽  
Rare Presentation ◽  
Case Presentation ◽  
Appropriate Treatment ◽  
Systemic Symptoms

Abstract Background Granulomatosis with polyangiitis (GPA) is an anti-neutrophilic cytoplasmic antibody-associated vasculitis affecting small to medium-sized vessels and involves most commonly the kidneys and the respiratory tract. Skin involvement can be seen in up to 50% of children with GPA and is the initial presenting symptom in 7.7%. Pyoderma gangrenosum (PG)-like ulcers are rarely described as a skin manifestation in GPA and very few cases have been reported previously in children. Case presentation We describe 3 new pediatric cases of GPA with PG-like ulcerations. The median age at first symptom was 15 years. Two patients had PG-like ulceration as their initial presentation; additional symptoms eventually led to the diagnosis of GPA 2–24 months later. In 1 case, proteinase 3 (PR3) was negative when first tested, but converted to positive when systemic symptoms emerged; in the other 2 cases PR3 was positive at presentation. All 3 patients had prominent facial lesions. None of the patients responded to treatment with antibiotics or medications commonly used to manage PG, including corticosteroids and cyclosporine. All patients had excellent responses to rituximab. An electronic database literature review was performed and 4 previously reported cases were identified. We assessed the clinical characteristics, serology, and response to treatment of the previously reported and our newly diagnosed cases. Conclusion PG-like ulceration is a rare presentation of pediatric GPA which may precede classic systemic GPA symptoms. The predominance of facial ulcer, granulomatous and neutrophilic inflammation on skin biopsy and lack of response to PG treatments are characteristic of GPA-associated PG-like ulcers. Our review suggests that treatment with rituximab may be needed to improve the skin lesions. Recognizing that PG-like ulcerations can occur in pediatric GPA may result in timely diagnosis, appropriate treatment and improved prognosis.

scholarly journals A rare presentation of giant cystic retroperitoneal teratoma in adult; A case report.

2019 ◽  
Vol 26 (10) ◽  
pp. 1805-1809
Author(s):  
Imran Aslam ◽  
Balakhsher Zaman ◽  
Mohammad Sohail Asghar
Keyword(s):  
Case Report ◽  
Ct Scan ◽  
Rare Case ◽  
Clinical Presentation ◽  
Middle Age ◽  
Thyroid Tissue ◽  
Rare Presentation ◽  
Case Presentation ◽  
Retroperitoneal Teratoma ◽  
Abdominal Fullness

Teratoma are bizarre tumors of germ cell and are usually present in testis and ovaries and contains structures like hairs, teeth, bone, thyroid tissue or more complex organs. Retroperitoneal occurrence is an uncommon site of presentation. They are usually present in childhood and rarely in adults. Here we are discussing a rare case presentation of middle age female, presented with abdominal fullness and pain which later diagnosed as retroperitoneal teratoma on CT scan. Clinical presentation, workup, surgical management, and outcome is discussed in this study.

scholarly journals Brucellar Pericarditis: You Can Get from Your Pet!

2020 ◽  
pp. 1-3
Author(s):  
Abeer M Shawky ◽  
Keyword(s):  
Infectious Disease ◽  
Rare Case ◽  
Clinical Presentation ◽  
Exceptional Case ◽  
Cardiac Symptom ◽  
Case Presentation ◽  
Night Sweats ◽  
Cardiac Manifestation ◽  
Mild Fever

Background: Brucellosis is a worldwide zoonotic systemic infectious disease with a diverse clinical presentation. Cardiovascular affections are not frequent, and the main cardiac manifestation of Bru-cellosis is endocarditis. Pericarditis without endocarditis is extremely rare. Case Presentation: In this case report, we present an exceptional case of pericarditis caused by Brucellosis in the absence of concomitant endocarditis in a 30-year-old woman, one-month postpar-tum, from the countryside. The lady presented with night sweats, mild fever, weight loss, dyspnea and chest pain. A diagnostic workup revealed positive titers for Brucella, indicating that the patient was suffering from systemic Brucellosis. The patient recovered completely, after receiving appropri-ate oral non-steroidal anti-inflammatory and dual antibiotics treatment, and responded well without any sign of relapse during a six month follow-up period. Conclusion: Pericarditis can occur during Brucellosis as an isolated cardiac symptom. Brucellar per-icarditis should always be kept in mind in patients with pericarditis and pericardial effusion, alt-hough the prevalence of pericarditis in Brucellosis is very low.

scholarly journals Giant epidermal inclusion cyst: an unusual case presentation

2016 ◽  
Vol 3 (1) ◽  
pp. 166
Author(s):  
Neha Salaria ◽  
Uma Garg ◽  
Anshul Singla
Keyword(s):  
Oral Cavity ◽  
Unusual Case ◽  
Clinical Presentation ◽  
Anatomical Variation ◽  
Inclusion Cyst ◽  
Diagnostic Dilemma ◽  
Case Presentation ◽  
Surgical Exploration ◽  
Histological Variant ◽  
Epidermal Inclusion Cyst

<p class="abstract">Epidermoids or epidermal inclusion cysts are developmental malformations rarely seen in the oral cavity. They are a histological variant of lesions broadly termed as dermoid cysts. The case discussed here stands out not only due to its unique clinical presentation which can put a clinician in a diagnostic dilemma but also because of its anatomical variation upon surgical exploration which can add to the conundrum<span lang="EN-IN">.</span></p><p class="abstract"> </p>

scholarly journals Scrotal calculi with delayed urethroscrotal fistula: a rare case presentation with literature review

2019 ◽  
Vol 6 (6) ◽  
pp. 2225
Author(s):  
Ramesh K. Aggarwal
Keyword(s):  
Literature Review ◽  
Rare Case ◽  
Clinical Presentation ◽  
Surgical Excision ◽  
Clinical Suspicion ◽  
Scrotal Skin ◽  
Rare Presentation ◽  
Case Presentation ◽  
Scrotal Swelling ◽  
Urethral Stone

Scrotal calculi are not so common entity in the clinical presentation. Scrotourethral fistula is an abnormal communication between scrotal skin and the urethra, usually result of the inflammation and due to perforation by urethral calculi and sometimes iatrogenic due to surgery done for urethral stone removal or uretheroplasty. We present here a very rare case of young adult gentleman who initially presented with a scrotal swelling, turned out into scrotal calculi while doing surgical excision, later on presented as uretheroscrotal fistula that managed conservatively. After going through the available literature and through the pub med articles (approx 148 articles while searching with titles of ‘scrotal calculi’, ‘scrotourethral fistula’, ‘uretherocutaneous fistula’) we found only 1-2 cases of scrotourethral fistula. A high index of clinical suspicion and examination is needed to diagnose such asymptomatic rare presentation cases.

scholarly journals Adrenocortical Carcinoma Presenting with Signs of Acute Abdomen

2013 ◽  
Vol 2013 ◽  
pp. 1-4 ◽  
Author(s):  
Dimitrios Symeonidis ◽  
Ioannis Chatzinikolaou ◽  
Georgios Koukoulis ◽  
Ioannis Mamaloudis ◽  
Konstantinos Tepetes
Keyword(s):  
Acute Abdomen ◽  
Adrenocortical Carcinoma ◽  
Clinical Presentation ◽  
Mass Effect ◽  
Emergency Laparotomy ◽  
Rare Presentation ◽  
Case Presentation ◽  
Life Threatening ◽  
Life Threatening Complication ◽  
Adrenocortical Carcinomas

Background. Adrenocortical carcinomas represent rare malignancies. In cases of hormone-secreting tumors, the hormone in excess determines the nearly diagnostic clinical presentation. Biologically inert tumors are diagnosed either due to the mass effect or incidentally. The purpose of the present study was to present an extremely rare presentation pattern of adrenocortical carcinoma.Case Presentation. We present the case of a 35-year-old female patient that underwent emergency laparotomy due to signs of acute abdomen and concomitant cardiovascular collapse caused by a spontaneously ruptured large adrenocortical carcinoma.Conclusion. Spontaneous rupture of an adrenocortical carcinoma presenting with signs of acute abdomen is an extremely rare clinical scenario. Increased level of suspicion is essential in order to diagnose and treat timely this life-threatening complication.

scholarly journals A Case Presentation on Acute Lymphonodular Pharyngitis with a Review

2021 ◽  
Vol 12 (1) ◽  
pp. 392-395
Author(s):  
Mohammed Malik Afroz ◽  
Karthiga Kannan ◽  
Chanchala H P ◽  
Priyanka Talwade ◽  
Avinash Tejasvi M L ◽  
...  
Keyword(s):  
Clinical Presentation ◽  
Early Years ◽  
Posterior Aspect ◽  
Prodromal Symptoms ◽  
Case Presentation ◽  
Detection And Identification ◽  
Dental Office ◽  
Mild Fever ◽  
Apparently Healthy

Acute lymphonodular pharyngitis is a viral infection predominantly caused by coxsackievirus and is seen in children. The infection is characterized by typical prodromal symptoms of mild fever, sore throat, difficulty in deglutition. The characteristic clinical presentation reveals multiple raised, discrete, yellowish-white non-vesicular lesions with surrounding erythematic appearance commonly seen on the roof of the posterior aspect of the oral cavity. The lesions have been identified as early as 1962, described in detail in the literature. These lesions may be common but are often overlooked due to less knowledge among the patients or rather the patients not directly reporting to the dental office. We present with a case of a five-year-old apparently healthy child with a detailed description of symptoms, clinical features, follow up, differential diagnosis and review. This article aims to bring awareness of the disease in the present form to the readers with the purpose of early detection and identification of condition for treatment. We found very less review in the literature over past years which bring us to understand that it is overlooked though it has been identified in the early years. The disease may be reported less, but it is not obsolete to be discarded.

scholarly journals OVARIAN VEIN THROMBOSIS;

2017 ◽  
Vol 24 (08) ◽  
pp. 1256-1258
Author(s):  
Muhammad Umar Younis
Keyword(s):  
Abdominal Pain ◽  
Lower Abdominal Pain ◽  
Exploratory Laparotomy ◽  
Ovarian Vein ◽  
Rare Presentation ◽  
Diagnostic Dilemma ◽  
Case Presentation ◽  
Vein Thrombosis ◽  
Prompt Diagnosis ◽  
Ovarian Vein Thrombosis

Introduction: Ovarian Vein Thrombosis is a rare presentation in the surgicalemergency. It usually is reported in the postpartum period but may present as an acuteabdomen in the ER. Case Presentation: A 38 years old female presented with a history ofDilation and Curettage 3 days back Presented with severe lower abdominal pain, fever andvomiting. An exploratory laparotomy revealed left ovarian thrombosis with 1L hemorrhagicfluid in the peritoneal cavity. Left oophorectomy was done and anticoagulation started post op.Conclusion: OVT poses a diagnostic dilemma for the patient presenting to the emergency withan acute abdomen because prompt diagnosis and treatment are necessary to prevent furthercomplications.

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