Lymphocytic hypophysitis: Report of an unusual case of a rare disorder

2001 ◽  
Vol 24 (3) ◽  
pp. 190-193 ◽  
Author(s):  
M. Durán Martínez ◽  
C. Santonja ◽  
I. Pavón de Paz ◽  
S. Monereo Megías
Keyword(s):  
Unusual Case ◽  
Lymphocytic Hypophysitis ◽  
Rare Disorder

scholarly journals Median Neuropathy After Blood Draw Mimics Painful Clenched Fist Syndrome in a Child

Hand ◽  
2019 ◽  
Vol 15 (2) ◽  
pp. NP31-NP36
Author(s):  
Elspeth J.R. Hill ◽  
Lorna C. Kahn ◽  
Lynne M. Sterni ◽  
Susan E. Mackinnon ◽  
John M. Felder
Keyword(s):  
Median Nerve ◽  
Unusual Case ◽  
Psychiatric Treatment ◽  
Conversion Disorder ◽  
Nerve Entrapment ◽  
Rare Disorder ◽  
Blood Draw ◽  
Hand Surgeon ◽  
Anatomic Basis ◽  
Multidisciplinary Pain Management

Background: Clenched fist syndrome is a rare disorder, often attributed to a conversion disorder without anatomic basis. Here, we review the literature surrounding clenched fist syndrome and challenge the assumption it is always psychiatric in origin, via description of a case of clenched fist syndrome responsive to surgical nerve decompression. Methods: An unusual case of clenched fist syndrome is reviewed and discussed. Results: A child presenting with clenched fist syndrome failed conservative measures consisting of formal hand therapy, multidisciplinary pain management, and psychiatric treatment. On clinical examination, she had findings consistent with median nerve entrapment. After undergoing surgical decompression of the median nerve in the forearm and carpal tunnel, the clenched fist resolved immediately. Conclusions: Nerve compression may be an unrecognized factor underlying some cases of clenched fist syndrome. Evaluation by a hand surgeon or a hand therapist skilled in the detection of peripheral nerve entrapment or injury should be considered as part of the workup for this rare disorder.

Lymphocytic hypophysitis: unusual features of a rare disorder

1995 ◽  
Vol 42 (5) ◽  
pp. 529-534 ◽  
Author(s):  
P. J. Jenkins ◽  
S. L. Chew ◽  
D. G. Lowe ◽  
F. Afshar ◽  
M. Charlesworth ◽  
...  
Keyword(s):  
Lymphocytic Hypophysitis ◽  
Rare Disorder

Idiopathic portal vein thrombosis not related to hepatic disease or malignancy

2021 ◽  
Vol 14 (11) ◽  
pp. e245620
Author(s):  
Samer Alkassis ◽  
Nathan Zaher ◽  
Zaid Kaloti ◽  
Diane Levine
Keyword(s):  
Portal Vein ◽  
Young Woman ◽  
Portal Vein Thrombosis ◽  
Unusual Case ◽  
Hepatic Disease ◽  
Rare Disorder ◽  
Abdominal Ct ◽  
Diagnostic Modality ◽  
Vein Thrombosis ◽  
Contrast Enhanced

Acute portal vein thrombosis (PVT) is a rare disorder defined by the sudden occlusion of the portal vein, which could be partial or complete. Prothrombotic states, inherited or acquired, are thought to be the cause in patients without cirrhosis or malignancy. However, the aetiology of some cases remains idiopathic despite a multidisciplinary diagnostic approach. The initial diagnostic modality to confirm PVT is either contrast-enhanced abdominal (CT) or MRI; as it can identify predisposing factors, and detect evidence of complications. Eliciting the underlying aetiology is critical to guide overall management and prevent future recurrence. The purpose of treatment is to stop thrombus extension and achieve portal vein patency by anticoagulation to optimise outcomes. Herein, we present an unusual case of spontaneous PVT in a young woman. We will also discuss the evaluation of patients without obvious aetiology.

scholarly journals A Rare Case Report of Extensive Polyostotic Gorham's Disappearing Bone Disease Involving the Upper Extremity

2011 ◽  
Vol 2011 ◽  
pp. 1-5 ◽  
Author(s):  
Elke R. Ahlmann ◽  
Yanling Ma ◽  
Vonny Tunru-Dinh
Keyword(s):  
Case Report ◽  
Upper Extremity ◽  
Bone Disease ◽  
Rare Case ◽  
Unusual Case ◽  
Rare Disorder ◽  
Extensive Disease ◽  
Rare Case Report ◽  
Gorham’S Disease ◽  
Disease Spreading

Gorham's disease is a rare disorder involving the proliferation of endothelial channels resulting in resorption and disappearance of bone. An unusual case of polyostotic Gorham's disease affecting the scapula, humerus, radius, and ulna in a 39-year-old woman is described. The patient had extensive disease spreading across both the glenohumeral and humeroulnar joints. This is the first report of Gorham's disease spreading across multiple joints in the upper extremity.

341 MANDIBULOACRAL DYSPLASIA: AN UNUSUAL CASE OF A RARE DISORDER.

2006 ◽  
Vol 54 (1) ◽  
pp. S138.5-S138
Author(s):  
T. H. Cushing ◽  
M. A. Manning ◽  
L. H. Seaver ◽  
J. M. Brumblay ◽  
H. E. Hoyme
Keyword(s):  
Unusual Case ◽  
Rare Disorder ◽  
Mandibuloacral Dysplasia

scholarly journals Coexistence of Giant Cell Arteritis with Aortitis and Sweet’s Syndrome: Is It a Coincidence?

2021 ◽  
pp. 9-13
Author(s):  
Abir Derbel ◽  
Chifa Damak ◽  
Mouna Snoussi ◽  
Faten Frikha ◽  
Slim Charfi ◽  
...  
Keyword(s):  
Giant Cell Arteritis ◽  
Giant Cell ◽  
Inflammatory Bowel Diseases ◽  
Unusual Case ◽  
Rare Disorder ◽  
Sweet’S Syndrome ◽  
Sweet's Syndrome ◽  
Bowel Diseases ◽  
Inflammatory Bowel ◽  
Rheumatoid Diseases

Sweet’s syndrome (SS) is a rare disorder characterized by dermal infiltration by neutrophils. It has been reported in association with drugs, malignancies, infections, rheumatoid diseases, inflammatory bowel diseases. Its association with giant cell arteritis (GCA) hasn’t been reported to our knowledge. The diagnosis of GCA was based on inflammatory biological syndrome with aortitis with negative infectious investigations. Herein, we present an unusual case of SS associated with GCA treated with steroids with good outcomes.

The Ultrastructure of Lymphocytic Hypophysitis

1981 ◽  
Vol 39 ◽  
pp. 466-467
Author(s):  
S.L. Asa ◽  
K. Kovacs ◽  
J. M. Bilbao ◽  
R. G. Josse ◽  
K. Kreines
Keyword(s):  
Electron Microscopy ◽  
Plasma Cells ◽  
Secretory Granules ◽  
Sella Turcica ◽  
Uranyl Acetate ◽  
Lymphocytic Hypophysitis ◽  
Pituitary Cells ◽  
Transmission Electron ◽  
Ultrathin Sections ◽  
Mass Lesions

Seven cases of lymphocytic hypophysitis in women have been reported previously in association with various degrees of hypopituitarism. We report two pregnant patients who presented with mass lesions of the sella turcica, clinically mimicking pituitary adenoma. However, pathologic examination revealed extensive infiltration of the anterior pituitary by lymphocytes and plasma cells with destruction of the gland. To our knowledge, the ultrastructural features of lymphocytic hypophysitis have not been studied so far.For transmission electron microscopy, tissue from surgical specimens was fixed in glutaraldehyde, postfixed in OsO4, dehydrated and embedded in epoxy-resin. Ultrathin sections were stained with uranyl acetate and lead citrate and examined with a Philips 300 electron microscope.Electron microscopy revealed adenohypophysial cells of all types exhibiting varying degrees of injury. In the areas of most dense inflammatory cell infiltration pituitary cells contained large lysosomal bodies fusing with secretory granules (Fig. 1), as well as increased numbers of swollen mitochondria, indicating oncocytic transformation (Fig. 2).

Variable erythrokeratoderma. An unusual case

1969 ◽  
Vol 100 (6) ◽  
pp. 744-748 ◽  
Author(s):  
F. G. Schellander
Keyword(s):  
Unusual Case

An unusual case of suntanning

1978 ◽  
Vol 114 (2) ◽  
pp. 287b-287
Author(s):  
G. P. Ream
Keyword(s):  
Unusual Case
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